A novel mutation in NDUFB11 unveils a new clinical phenotype associated with lactic acidosis and sideroblastic anemia

01 Pubblicazione su rivista
Torraco Alessandra, Bianchi Marzia, Verrigni Daniela, Gelmetti Vania, Riley Lisa, Niceta Marcello, Martinelli Diego, Montanari Arianna, Guo Yiran, Rizza Teresa, Diodato Daria, Di Nottia Michela, Lucarelli Barbarella, Sorrentino Francesco, Piemonte Fiorella, Francisci Silvia, Tartaglia Marco, Valente Enza Maria, Dionisi Vico Carlo, Christodoulou John, Bertini Enrico, Carrozzo Rosalba
ISSN: 1399-0004

NDUFB11, a component of mitochondrial complex I, is a relatively small integral membrane protein, belonging to the 'supernumerary' group of subunits, but proved to be absolutely essential for the assembly of an active complex I. Mutations in in the X-linked nuclear encoded NDUFB11 gene have recently been discovered in association with two distinct phenotypes, i.e. microphthalmia with linear skin defects and histiocytoid cardiomyopathy. We report on a male with complex I deficiency, caused by a de novo mutation in NDUFB11 and displaying early onset sideroblastic anemia as the unique feature. This is the third report that describes a mutation in NDUFB11 but all are associated to a different phenotype. Our results further expand the molecular spectrum and associated clinical phenotype of NDUFB11 defects.

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